Gene Information

FBN1

fibrillin 1 [Source:HGNC Symbol;Acc:HGNC:3603]

protein_codingChromosome 15ENSG00000166147

Overview

FBN1 variants are associated with 11 diseases including familial thoracic aortic aneurysm and aortic dissection and Shprintzen-Goldberg syndrome and 9 others, with 446 documented clinical phenotypes.


Associated Diseases

The FBN1 gene is associated with 11 medical conditions, including:

familial thoracic aortic aneurysm and aortic dissection

MONDO:0019625

Shprintzen-Goldberg syndrome

MONDO:0008426

progeroid and marfanoid aspect-lipodystrophy syndrome

MONDO:0014831

Weill-Marchesani syndrome 2, dominant

MONDO:0012013

Marfan syndrome

MONDO:0007947

geleophysic dysplasia

MONDO:0000127

Acromicric dysplasia

MONDO:0007055

Weill-Marchesani syndrome

MONDO:0018096

stiff skin syndrome

MONDO:0008492

neonatal Marfan syndrome

MONDO:0017309

isolated ectopia lentis

MONDO:0015998


Clinical Phenotypes

Research has identified 446 phenotypic features associated with FBN1 variants:

Ptosis

HP:0000508

Bruising susceptibility

HP:0000978

Prominent forehead

HP:0011220

Joint stiffness

HP:0001387

Knee flexion contracture

HP:0006380

Spondylolisthesis

HP:0003302

Lens luxation

HP:0012019

Prominent forehead

HP:0011220

Pulmonary artery dilatation

HP:0004927

Hypertelorism

HP:0000316

Camptodactyly of toe

HP:0001836

Severe short stature

HP:0003510

Mitral valve prolapse

HP:0001634

Narrow palate

HP:0000189

Platyspondyly

HP:0000926

View all


ClinVar Variants

ClinVar contains 10 variants associated with FBN1. Below are some notable variants:

NM_000138.5(FBN1):c.7631C>A (p.Thr2544Asn)

Uncertain significance

VCV004528264

Review: criteria provided, single submitter

NM_000138.5(FBN1):c.5224+5G>C

Uncertain significance

VCV004527341

Review: criteria provided, single submitter

NM_000138.5(FBN1):c.358A>G (p.Asn120Asp)

Uncertain significance

VCV004526958

Review: criteria provided, single submitter

NM_000138.5(FBN1):c.5556del (p.Glu1852fs)

Likely pathogenic

VCV004526733

Review: criteria provided, single submitter

NM_000138.5(FBN1):c.3839-3C>G

Uncertain significance

VCV004526479

Review: criteria provided, single submitter


Recent Publications

There are 1,075 publications about FBN1 indexed in PubMed. Below are some recent papers:

Identification of pathogenic variants for the development of ultra-long axial length in myopic children.

Zhu Y, Li X, Chen Y

PMID: 41259386

2025

PLoS One

Associations between asprosin, insulin resistance, and oxidative stress in adults with obesity.

Kościuszko M, Buczyńska A, Duraj E

PMID: 41258265

2025 Nov 19

Sci Rep

A diagnostic RNA sequencing assay for direct identification and interpretation of pathogenic variants in the FBN1 gene.

Irshaid M, Al Mansoori G, Sulaiman M

PMID: 41256009

2025

Front Mol Biosci

[Marfan Syndrome After Undergoing Genetic Testing Related to the Aorta, Following a Staged Total Aortic Replacement].

Kogure K, Nunokawa M, Inaba Y

PMID: 41253327

2025 Oct

Kyobu Geka

Genetic Burden in Congenital Anomalies of the Mitral and Tricuspid Valves: A Case-Control Study.

Campos-Garcia FJ, Castillo-Espinola AM, Medina-Escobedo CE

PMID: 41247545

2025 Nov 17

Pediatr Cardiol

View all 1,075 publications on PubMed →

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Trusted Data Sources

EnsemblMonarch InitiativeClinVarGeneReviewsPubMed

Last updated: 11/20/2025

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